儿童异位支气管源性囊肿2例并文献复习

Ectopic bronchogenic cysts in children:a report of 2 cases with a literature review

目的探讨异位支气管源性囊肿的临床特征、诊治特点。方法回顾性分析青岛市妇女儿童医院2020年1月至2022年6月收治的2例异位支气管源性囊肿患儿的病历资料,病例1为家属偶然发现体表肿物就诊,病例2为患儿体检时发现,2例患儿均无特异性临床表现,均行肿物切除术,术后病理考虑支气管源性囊肿。以"异位支气管源性囊肿(ectopic bronchogenic cysts)"、"支气管源性囊肿(bronchogenic cysts)"为关键词,检索PubMed、中国知网、万方数据库截至2022年10月的文献并进行文献复习。结果患儿术后均顺利恢复,随访1年以上未见复发。文献检索发现儿童报道病例较成人少见,中文报道儿童异位支气管源性囊肿39例,其中最多见于颈至胸骨上部位;英文文献报道儿童异位支气管源性囊肿77例,其中多见于肩胛处。结论异位支气管源性囊肿术前不易明确诊断,手术切除囊肿患儿预后良好。

Objective To explore the clinical features,diagnosis and treatment of ectopic bronchogenic cysts.Methods The relevant medical records were retrospectively reviewed for 2 children hospitalized with ectopic bronchogenic cysts from January 2020 to June 2022.One case of body surface mass was accidentally found while another case detected during physical examination.Both had non-specific clinical manifestations and underwent mass resection.And bronchogenic cyst was confirmed after postoperative pathology.With"ectopic bronchogenic cysts"and"bronchogenic cysts"as key words,the literature items were retrieved from the databases of PubMed,China National Knowledge Network and Wanfang up to October 2022.Results All children recovered successfully after surgery and no recurrence was noted during a follow-up period of more than 1 year.Literature searching revealed that the reported cases in children were less common than those in adults.There were 39 Chinese cases of ectopic bronchogenic cysts in children.Most cases originated from neck to suprasternum.And 77 pediatric cases of ectopic bronchogenic cysts were reported in English.Most cases were located in scapula.Conclusions Ectopic bronchogenic cyst is not easily diagnosed before surgery.After resection,the prognosis is generally ecellent.