Dear Sir, I am Dr. Boyun Kim, form the Department of Ophthalmology, Bucheon St. Mary’s Hospital, Bucheon, Korea. I write to present a case report of apocrine hidrocystoma on temporal bulbar conjunctiva. Apocrine hidr...Dear Sir, I am Dr. Boyun Kim, form the Department of Ophthalmology, Bucheon St. Mary’s Hospital, Bucheon, Korea. I write to present a case report of apocrine hidrocystoma on temporal bulbar conjunctiva. Apocrine hidrocystoma (AH) is a benign cutaneous cystic nodule arising from apocrine glands of Moll [1]. This lesion usually occurs on eyelids and canthus [1,2], ears, chest, shoulders in adults but its occurrence in conjunctiva [3] is展开更多
Background:Hidrocystoma,or sudoriferous cyst,is an eyelid tumor originating from apocrine or eccrine sweat glands.Its presence in the orbit is relatively rare.Case presentation:A full-term female child with severe rig...Background:Hidrocystoma,or sudoriferous cyst,is an eyelid tumor originating from apocrine or eccrine sweat glands.Its presence in the orbit is relatively rare.Case presentation:A full-term female child with severe right eye extrusion was referred to our department two hours after birth.We performed cyst aspiration under ultrasonic guidance;15 cc straw-colored fluid was obtained and proptosis resolved significantly.Orbital magnetic resonance imaging(MRI)showed a large unilocular retrobulbar mass with hypo-intensity in T1 and hyper-intensity in T2.The case underwent further daily ocular assessment until day 5;when proptosis began to worsen again.On day 6,under general anesthesia,we performed aspiration and then the cyst was completely removed with an intact wall through a trans-conjunctival incision.The diameter of the aspirated cyst was about 4 cm.In pathologic consultation,a cystic cavity lined by a layer of sweat duct like epithelium with apical snouts consistent with the diagnosis of apocrine hidrocystoma was reported.Conclusion:To date,in the literature,six other cases of orbital hidrocystoma have been reported in childhood with protean clinical pictures;none of which presented at birth.Herein,we introduce the first case report at birth and also provide a review on the literature.Our report strongly argues against the well reputed theory of traumatic origin for orbital hidrocystoma;it has been postulated that this tumor may be the result of sweat gland cells implantation through the orbit.We thereby suggest the possible presence of choristomatous ectopic sweat gland cells in the orbit during embryogenesis.展开更多
文摘Dear Sir, I am Dr. Boyun Kim, form the Department of Ophthalmology, Bucheon St. Mary’s Hospital, Bucheon, Korea. I write to present a case report of apocrine hidrocystoma on temporal bulbar conjunctiva. Apocrine hidrocystoma (AH) is a benign cutaneous cystic nodule arising from apocrine glands of Moll [1]. This lesion usually occurs on eyelids and canthus [1,2], ears, chest, shoulders in adults but its occurrence in conjunctiva [3] is
文摘Background:Hidrocystoma,or sudoriferous cyst,is an eyelid tumor originating from apocrine or eccrine sweat glands.Its presence in the orbit is relatively rare.Case presentation:A full-term female child with severe right eye extrusion was referred to our department two hours after birth.We performed cyst aspiration under ultrasonic guidance;15 cc straw-colored fluid was obtained and proptosis resolved significantly.Orbital magnetic resonance imaging(MRI)showed a large unilocular retrobulbar mass with hypo-intensity in T1 and hyper-intensity in T2.The case underwent further daily ocular assessment until day 5;when proptosis began to worsen again.On day 6,under general anesthesia,we performed aspiration and then the cyst was completely removed with an intact wall through a trans-conjunctival incision.The diameter of the aspirated cyst was about 4 cm.In pathologic consultation,a cystic cavity lined by a layer of sweat duct like epithelium with apical snouts consistent with the diagnosis of apocrine hidrocystoma was reported.Conclusion:To date,in the literature,six other cases of orbital hidrocystoma have been reported in childhood with protean clinical pictures;none of which presented at birth.Herein,we introduce the first case report at birth and also provide a review on the literature.Our report strongly argues against the well reputed theory of traumatic origin for orbital hidrocystoma;it has been postulated that this tumor may be the result of sweat gland cells implantation through the orbit.We thereby suggest the possible presence of choristomatous ectopic sweat gland cells in the orbit during embryogenesis.
